TY - JOUR
AU - Furthmann, Nikolas
AU - Bader, Verian
AU - Angersbach, Lena
AU - Blusch, Alina
AU - Goel, Simran
AU - Sánchez-Vicente, Ana
AU - Krause, Laura J.
AU - Chaban, Sarah A.
AU - Grover, Prerna
AU - Trinkaus, Victoria A.
AU - van Well, Eva M.
AU - Jaugstetter, Maximilian
AU - Tschulik, Kristina
AU - Damgaard, Rune Busk
AU - Saft, Carsten
AU - Ellrichmann, Gisa
AU - Gold, Ralf
AU - Koch, Arend
AU - Englert, Benjamin
AU - Westenberger, Ana
AU - Klein, Christine
AU - Jungbluth, Lisa
AU - Sachse, Carsten
AU - Behrends, Christian
AU - Glatzel, Markus
AU - Hartl, F. Ulrich
AU - Nakamura, Ken
AU - Christine, Chadwick W.
AU - Huang, Eric J.
AU - Tatzelt, Jörg
AU - Winklhofer, Konstanze F.
TI - NEMO reshapes the α-Synuclein aggregate interface and acts as an autophagy adapter by co-condensation with p62
JO - Nature Communications
VL - 14
IS - 1
SN - 2041-1723
CY - [London]
PB - Nature Publishing Group UK
M1 - FZJ-2024-00271
SP - 8368
PY - 2023
AB - NEMO is a ubiquitin-binding protein which regulates canonical NF-κB pathwayactivation in innate immune signaling, cell death regulation and host-pathogeninteractions. Here we identify an NF-κB-independent function of NEMO inproteostasis regulation by promoting autophagosomal clearance of proteinaggregates. NEMO-deficient cells accumulate misfolded proteins upon proteotoxicstress and are vulnerable to proteostasis challenges. Moreover, apatient with a mutation in the NEMO-encoding IKBKG gene resulting indefective binding of NEMO to linear ubiquitin chains, developed a widespreadmixed brain proteinopathy, including α-synuclein, tau and TDP-43 pathology.NEMO amplifies linear ubiquitylation at α-synuclein aggregates and promotesthe local concentration of p62 into foci. In vitro, NEMO lowers the thresholdconcentrations required for ubiquitin-dependent phase transition of p62. Insummary, NEMO reshapes the aggregate surface for efficient autophagosomalclearancebyprovidingamobilephase at theaggregate interphase favoringcocondensationwith p62.
LB - PUB:(DE-HGF)16
C6 - 38114471
UR - <Go to ISI:>//WOS:001131904500002
DO - DOI:10.1038/s41467-023-44033-0
UR - https://juser.fz-juelich.de/record/1020576
ER -